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Tuberculosis & Respiratory Diseases

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Vol.74 No.1
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A Case of Congenital Cystic Adenomatoid Malformation Infected with Mycobacterium avium-intracellulare Complex

Tuberculosis & Respiratory Diseases / Tuberculosis & Respiratory Diseases,
2013, v.74 no.1, pp.28-31
Yong Jin Kim (Konkuk University School of Medicine)
Do Young Kim (Konkuk University)
Jung Woong Seo (Konkuk University School of Medicine)
Song Am Lee (Konkuk University)



Yong, J. K. , Do, Y. K. , Jung, W. S. , Song, A. L. , & (2013). A Case of Congenital Cystic Adenomatoid Malformation Infected with Mycobacterium avium-intracellulare Complex. Tuberculosis & Respiratory Diseases, 74(1), 28-31.
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Abstract

We present a case of congenital cystic adenomatoid malformation (CCAM) in a 25-year-old male who was presented with chronic cough. Chest radiography revealed an abnormal mass-like shadow in the right lower pulmonary zone. A contrast enhanced computed tomography showed an 11 cm solid, cystic mixed mass on the right lower lobe. A right lower lobectomy was performed by video-assisted thoracoscopic surgery without complications. The gross specimen showed a massive cavitation with multiloculated cysts of varying size, consistent with CCAM, along with noticeable granulomatous inflammation. Non-tuberculosis mycobacteria were isolated from a bronchial wash specimen, and the resected tissue homogenates were positive for Mycobacterium avium-intracellulare complex by polymerase chain reaction.

keywords
Cystic Adenomatoid Malformation of Lung, Congenital, Nontuberculous Mycobacteria, Mycobacterium avium Complex

Reference

1.

Laberge JM, Flageole H, Pugash D, Khalife S, Blair G, Filiatrault D, et al. Outcome of the prenatally diagnosed congenital cystic adenomatoid lung malformation: a Canadian experience. Fetal Diagn Ther 2001;16: 178-86.

2.

Ch'In KY, Tang MY. Congenital adenomatoid malformation of one lobe of a lung with general anasarca. Arch Pathol (Chic) 1949;48:221-9.

3.

Stocker JT, Madewell JE, Drake RM. Congenital cystic adenomatoid malformation of the lung: classification and morphologic spectrum. Hum Pathol 1977;8:155-71.

4.

Fromont-Hankard G, Philippe-Chomette P, Delezoide AL, Nessmann C, Aigrain Y, Peuchmaur M. Glial cell- derived neurotrophic factor expression in normal human lung and congenital cystic adenomatoid malformation. Arch Pathol Lab Med 2002;126:432-6.

5.

Kaslovsky RA, Purdy S, Dangman BC, McKenna BJ, Brien T, Ilves R. Bronchioloalveolar carcinoma in a child with congenital cystic adenomatoid malformation. Chest 1997;112:548-51.

6.

Benouaich V, Marcheix B, Begueret H, Brouchet L, Velly JF, Jougon J. Malignancy of congenital cystic adenomatoid malformation of lung in aged. Asian Cardiovasc Thorac Ann 2009;17:634-6.

7.

Nur S, Badr R, Sandoval C, Brudniki A, Yeh A. Syndromic presentation of a pleuropulmonary blastoma associated with congenital cystic adenomatoid malformation: a case report. J Pediatr Surg 2007;42:1772-5.

8.

Lin SH, Lee LN, Chang YL, Lee YC, Ding LW, Hsueh PR. Infected bronchogenic cyst due to Mycobacterium avium in an immunocompetent patient. J Infect 2005; 51:e131-3.

9.

Sparks JD, Das BB, Eid NS, Austin EH, Recto M. Atypical mycobacterial infection in sequestrated lung in an infant presenting with chronic pneumonitis and recurrent wheezing. Congenit Heart Dis 2008;3:284-7.

10.

Mooney LR, Brown JW 3rd, Saunders RL Jr. Intralobar pulmonary sequestration infected with a mycobacterium of the Battey-avium complex. Chest 1975;68:594- 5.

11.

Shiota Y, Arikita H, Aoyama K, Horita N, Hiyama J, Ono T, et al. Pulmonary sequestration associated by Mycobacterium intracellulare infection. Intern Med 2002;41:990-2.

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